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Depressive Symptoms in Children and Adolescents with Chronic Physical Illness: An Updated Meta-Analysis

Martin Pinquart, PHD, and Yuhui Shen, CAND PSYCH

Department of Psychology, Philipps University

All correspondence concerning this article should be addressed to Martin Pinquart, PHD, Department of

Psychology, Philipps University, D-35032 Marburg, Germany. E-mail: pinquart@staff.uni-marburg.de

Received July 8, 2010; revisions received and accepted October 20, 2010

Objective To integrate results of available studies that compared levels of depressive symptoms of children

and adolescents with chronic physical illness to healthy peers or test norms. Methods Random-effects

meta-analysis was computed with 340 studies and 450 subsamples. Results Children and adolescents

with chronic illness have, on average, higher levels of depressive symptoms than their healthy peers (d¼ .19

SD units). Differences are strongest for chronic fatigue syndrome (d¼ .94), fibromyalgia (d¼ .59), cleft lip

and palate (d¼ .54), migraine/tension head ache (d¼ .51), and epilepsy (d¼ .39). Larger effect sizes were

found in studies with higher proportion of girls, with a healthy control group, from developing countries,

published before 1990, and that used parent rating or clinician ratings rather than child

ratings. Conclusions Pediatricians and others working with children with chronic illnesses should screen

children with chronic physical illness for symptoms of psychological distress and make appropriate referrals

for mental health services, when needed.

Key words chronic illness; depression; meta-analysis; psychological functioning; psychological health.

In the United States, the number of children and adoles-

cents with chronic health conditions has increased dramat-

ically in the past four decades (Perrin, Bloom, &

Gortmaker, 2007). Although results from epidemiological

studies differ considerably, an overview of articles found

that, on average, 15% of children and adolescents have a

chronic health condition (van der Lee, Mokkink,

Grootenhuis, Heymans, & Offringa, 2007).

Chronic illness is a risk factor for psychological prob-

lems, such as depressive symptoms (e.g., Bennett, 1994).

For example, the presence of physical symptoms, such as

pain and fatigue, combined with the need for disease man-

agement regimes, are likely to interfere with many aspects

of daily life, such as regular school attendance and main-

taining peer relations, and may cause frustration (e.g.,

Suris, Michaud, & Viner, 2004). Children with chronic

illness may feel different from his peers and experience

peer rejection, which may have detrimental effects on

their self-concept (e.g., Sandstrom & Schanberg, 2004).

In addition, chronic illnesses may foster inappropriate

parental attitudes and behaviors, ranging from overprotec-

tion to rejection, which may impair psychological

well-being (e.g., Holmbeck et al., 2002). In some cases,

poor prognosis may cause feelings of helplessness and

hopelessness. Finally, side effects of treatments may

cause psychological distress (e.g., Miller et al., 2008).

A meta-analysis by Bennett (1994) on 60 statistical

effects from 46 studies found that children and adolescents

with chronic medical problems have elevated levels of de-

pressive symptoms, but differences with test norms or

healthy control groups were small (mean d¼ .27 SD

units). Because (a) the number of studies has increased

considerably since this meta-analysis, (b) the effects of

chronic illness on depressive symptoms may have changed

over time, and (c) the previous meta-analysis could not test

for moderating effects of many study characteristics, the

Journal of Pediatric Psychology 36(4) pp. 375–384, 2011 doi:10.1093/jpepsy/jsq104

Advance Access publication November 18, 2010 Journal of Pediatric Psychology vol. 36 no. 4 � The Author 2010. Published by Oxford University Press on behalf of the Society of Pediatric Psychology.

All rights reserved. For permissions, please e-mail: journals.permissions@oup.com

goal of the present study was to provide an updated

meta-analysis on the association between chronic physical

illness and depressive symptoms in children and

adolescents.

Depressive symptoms have to be distinguished from a

depressive disorder, such as major depression. Rating

scales assess depressive symptoms as a continuous vari-

able, and scores above defined cutoffs on valid scales

would imply a depressive disorder. However, depression

diagnosis is based on a clinical interview, and a number

of symptoms have to be present during a specified time

period (Emslie & Mayers, 1999). Because about 90% of the

available studies with chronically ill children used depres-

sion rating scales rather than clinical diagnoses, the present

meta-analysis focuses on depressive symptoms.

Research Questions

In the first research question we ask whether children and

adolescents with chronic physical illnesses have elevated

levels of depressive symptoms, and whether this would

differ between illnesses. Some authors have argued that

the nature of the child’s disorder is not important in de-

termining its psychological consequences, because chil-

dren with chronic physical disorders face common life

experiences and problems based on generic dimensions

of their conditions, rather than on idiosyncratic character-

istics of any specific disease entity (e.g., Stein & Jessop,

1982). Other authors have suggested that certain illness

characteristics or parameters may be more related to de-

pressive symptoms, such as neurologically related illnesses

(e.g., epilepsy; Plioplys, 2003), characteristics of illnesses

that have social implications (e.g., cosmetic effects, e.g.,

cleft lip; De Sousa, Devare, & Ghanshani, 2009), and

chronic pain (Eccleston, Crombez, Scotford, Clinch, &

Connell, 2004). Bennett (1994) reported moderate effect

sizes for asthma (d¼ .54) and sickle cell disease (d¼ .48),

a small effect size for diabetes (d¼ .22), and no elevated

levels of depressive symptoms in young people with cancer

(d¼ .00) and cystic fibrosis (d¼–.04). However, due to

the small number of studies per type of illness

(N¼4–13), effect sizes were not tested to see if they dif-

fered significantly from zero or if illnesses differed from one

another.

In the second research question we analyze whether

the effect sizes would differ by other study characteristics.

Age

On the one hand, depressive symptoms are more common

in adolescence than in childhood, and adolescents may be

confronted with more illness-related stressors than chil-

dren (e.g., when chronic illnesses hinder the development

of peer groups and intimate relationships; Suris et al.,

2004). On the other hand, adolescents might also have

better coping abilities (e.g., because of higher cognitive

abilities; Skinner & Zimmer-Gembeck, 2007). Thus, aver-

age age differences in the association between chronic ill-

ness and depressive symptoms are probably small. Bennett

(1994) reported that age was generally unrelated to depres-

sive symptoms, but he did not provide results from a

statistical test of age differences.

Gender

On average, female adolescents are more likely than males

to react to stressors with depressive symptoms (Piccinelli

& Wilkinson, 2000), which could lead to stronger effects

of chronic illness on depressive symptoms. Bennett (1994)

reported that the results of individual studies were incon-

sistent but he did not formally test for gender differences.

Race/Ethnicity

Because it is less clear whether race/ethnicity would mod-

erate the size of between-group differences, we did not

state a hypothesis.

Country

Because young people from industrialized, developed

countries may have better access to health care than their

peers from developing countries, we expected finding

lower between-group differences in depressive symptoms

in developed countries.

Year of Publication

Progress in the treatment of many diseases (e.g., Bleyer,

2002) and the development of services for young people

with chronic illness may lead to lower between-group

differences in more recent studies.

Rater and Assessment Methods

Bennett (1994) found higher between-group differences in

parent-rated depressive symptoms (d¼0.58) than in

self-rated depressive symptoms (d¼0.02), which may

either indicate that young patients tend to underreport

their psychological symptoms or that parents underesti-

mate their children’s ability to adapt to their illness.

Differences between raters were also expected to lead to

higher levels of depressive symptoms in young people with

chronic illnesses in studies that used parent ratings as a

measure of depressive symptoms (e.g., the Affective

Problems scale of the Child Behavior Checklist (CBCL);

376 Pinquart and Shen

Achenbach, Dumenci, & Rescorla, 2003) than in studies

that used self-reports of the child.

Duration of Illness

A longer duration of the disease gives more time for

psychological adaptation, but may also lead to an accumu-

lation of negative illness-related consequences, such as the

effect of repeated school absence on grades. Thus, we did

not state a specific hypothesis.

Study Quality

Associations of chronic illness with depressive symptoms

may be stronger in clinical convenience samples than in

representative community-based samples, because clinical

samples may overrepresent highly distressed young people

seeking treatment for their chronic disease. Similarly, the

size of between-group differences in depressive symptoms

may vary between studies that used groups matched on

sociodemographic variables and studies that did not con-

trol for these between-group differences, because the lack

of control for demographic variables may cause unsyste-

matic bias rather than a general overestimation or under-

estimation of between-group differences in depressive

symptoms.

Target of Comparison

Finally, between-group differences may be larger in studies

that compared children with chronic illnesses to healthy

peers than in studies that compared depressive symptoms

of chronically ill children to test norms, because the norm

population probably includes some children with chronic

illnesses. In fact, Bennett (1994) found such a difference

(d¼0.67 vs. d¼0.02).

Methods Sample

Studies were identified from the literature through elec-

tronic databases [PSYCINFO, MEDLINE, Google Scholar,

PSNYDEX (an electronic data base of psychological litera-

ture from German-speaking countries)—search terms:

(chronic illness or disability or aids or arthritis or asthma

or cancer or cleft or chronic fatigue syndrome or cystic

fibrosis or diabetes or fibromyalgia or hemophilia or hear-

ing impairment or HIV or epilepsy or inflammatory bowel

disease or migraine or rheumatism or sickle cell or spina

bifida or visual impairment) and (children or adolescents

or adolescence) and (depression or depressive or mental

health or psychological health)], and cross-referencing.

Criteria for inclusion of studies in the present

meta-analysis were:

(a) the studies have been published before September,

2010,

(b) they compared the levels of depressive symptoms

or the frequency of depression diagnoses between

children and adolescents with chronic physical ill-

ness and their healthy peers or test norms, or they

provided sufficient information for a comparison

with established normative data (e.g., by reporting

standardized T-scores),

(c) mean age of participants �18 years, and

(d) standardized between-group differences in depres-

sive symptoms were reported or could be

computed.

Documentation of physician diagnosis within each study

was not a requirement, because of the need to include

broad-based survey studies for which medical documenta-

tion might not be available. However, studies were excluded

if they focused on young people with chronic illnesses that

have been referred to psychological services due to depres-

sive symptoms, or if sufficient information for computing

effect sizes was not reported. In order to include studies

from different regions around the world, we also did not

limit the included studies to those written in English.

Available unpublished studies were also included.

Approximately 25% of the total number of studies

surveyed were eliminated, mainly because they did not

assess depressive symptoms or depression diagnosis

(14%), provided insufficient information about the effect

sizes (4%), did not exclusively focus on children and ado-

lescents with chronic physical illnesses (3%), had an aver-

age age of participants >18 years (1%), duplicated results

of previously published studies (1%), or were not available

via interlibrary loan (1%). After the exclusion of such stud-

ies, we were able to include 340 studies in the

meta-analysis that provided results for 450 subsamples.

The studies included are listed in the Appendix S1 (see

the Supplementary Data).

We entered the number of patients and control group

members, mean age, percentage of girls and of members of

ethnic minorities, the country of data collection, year of

publication, type of illness, duration of illness, the sam-

pling procedure (1¼probability samples, 0¼convenience

samples), the use of a control group (0¼yes, 1¼compar-

ison with test norms), equivalence of patients and control

group (1¼yes, 2¼not tested, 3¼no), the rater of depres-

sive symptoms (1¼child, 2¼parent, 3¼ teacher, 4¼cli-

nician), the measurement of the variables, and the

standardized size of between-group differences in

Depression and Chronic Illness 377

depressive symptoms. If between-group differences were

provided for several subgroups within the same publication

(e.g., for different illnesses), we entered them separately in

our analysis instead of entering the global association.

If data from more than one rater were collected, we entered

the effect sizes separately because we were interested in

whether the effect size would vary by the source of infor-

mation. However, in order to avoid a disproportional

weight of these studies, we adjusted the weights of the

individual effect sizes so that the sum of the weights of

the effect sizes was equal to the weight of the study if

only one effect size had been reported (Lipsey & Wilson,

2001). Based on one third of the coded studies, a mean

inter-rater reliability of 93% (range 86–100%) was

established.

Measures

Depressive symptoms were most often assessed with the

Child Depression Inventory (CDI; Kovacs, 1992; 203 sam-

ples), structured clinical interviews (46 samples), the Beck

Depression Inventory/Beck Youth Inventory (Beck, Beck,

& Jolly, 2001; 41 samples), the Behavior Assessment

System for Children (Reynolds & Kamphaus, 2004;

39 samples), the Affective Problems scale of the CBCL

(13 samples), and the depression scale of the Minnesota

Multiphasic Personality Inventory (MMPI) (Tellegen et al.,

2003; 10 samples).

Information from the World Bank (2010) was used for

coding countries as developed or developing/threshold

countries.

Statistical Integration of the Findings

Calculations for the meta-analysis were performed in six

steps, using random-effects models and the method of mo-

ments (for computations, see Lipsey & Wilson, 2001).

1. We computed effect sizes d for each study as the

difference in depressive symptoms between the

sample with chronic illness and the control

sample divided by the pooled SD. If the authors

provided only test scores for children and adoles-

cents with chronic illness, we used the norms

from the test manual for comparison. However,

because Twenge and Nolen-Hoeksema (2002) pro-

vided norms for the CDI based on a much larger

sample than the original manual (Kovacs, 1992),

we used the norms by Twenge and

Nolen-Hoeksema (2002). Outliers that were more

than two SD from the mean of the effect sizes

were recoded to the value at two SD (Lipsey &

Wilson, 2001).

2. Effect size estimates were adjusted for bias due to

overestimation of the population effect size in

small samples.

3. Weighted mean effect sizes and 95% confidence

intervals (95% CIs) were computed. The signifi-

cance of the mean was tested by dividing the

weighted mean effect size by the SE of the mean.

To interpret the practical significance of the re-

sults, we used the Binomial Effect Size Display

(BESD; Rosenthal & Rubin, 1982) and Cohen’s

criteria (Cohen, 1988). According to Cohen, differ-

ences of d� .8 are interpreted as large, of

d¼ .50–.79 as medium, and of d¼ .20–.49 as

small.

4. For testing whether the results may be influenced

by publication bias (a trend for nonsignificant re-

sults not being published), we used the ‘‘trim and

fill’’ algorithm (Duval & Tweedie, 2000), which

estimates an adjusted effect size in the presence of

publication bias.

5. Homogeneity of effect sizes was computed by use

of the Q statistic.

6. In order to test the influence of moderator vari-

ables, we used an analogue of analysis of variance

and weighted ordinary least squares regression

analyses.

Results

Data from 33,047 children and adolescents with chronic

illnesses were included. The largest subgroups had asthma

(N¼9,274), diabetes (N¼4,058), cancer (N¼3,400), mi-

graine or tension-type head ache (N¼2,300), and epilepsy

(N¼2,096). The participants had a mean age of 12.6 years

(SD¼2.6 years); 50.2% of them were girls and 32.5% were

members of ethnic minorities.

On average, children and adolescents with chronic

physical illnesses had higher levels of depressive symptoms

than their healthy peers—a small to very small effect

(Table I). According to the BESD, 54.8% of children with

chronic illnesses and 45.2% of their healthy peers would

show depressive symptoms above the median. The

trim-and-fill algorithm did not find any evidence for a

file-drawer problem, and the original effect size remained

unchanged after applying this procedure.

We computed separate effects in cases where at least

five studies were available for a particular chronic disease.

Separate effect sizes could be computed for 16 illnesses.

Strongest between-group differences were found for

chronic fatigue syndrome, fibromyalgia, migraine/tension

378 Pinquart and Shen

Table I. Differences in Depression between Children with and without Chronic Illness: Univariate Analysis of Moderator Variables

Total difference

k d 95% CI Z Qw 450 .19 0.15 to 0.23 9.28*** 577.72***

Kind of illness QB(15,433)¼114.31***

Arthritis/rheumatism 24 �.08 �0.26 to 0.10 �0.89 27.25

Asthma 56 .12 0.01 to 0.23 2.21* 66.52

Cancer 62 �.07 �0.18 to 0.04 �1.21 53.65

Chronic fatigue syndrome 14 .94 0.67 to 1.213 6.90*** 13.62

Chronic migraine/tension-type head ache 22 .51 0.32 to 0.70 5.25*** 15.32

Cleft lip and palate 7 .54 0.21 to 0.86 3.23** 11.78

Cystic fibrosis 15 �.05 �0.27 to 0.18 �0.41 6.96

Diabetes 57 .09 �0.02 to 0.20 1.55 65.51

Epilepsy 32 .39 0.24 to 0.54 5.09*** 35.86

Fibromyalgia 10 .59 0.30 to 0.87 4.06*** 10.50

HIV infection/AIDS 9 �.02 �0.30 to 0.26 �0.15 2.61

Heart disease 5 .23 �0.15 to 0.62 1.19 3.90

Inflammatory bowel disease 14 .18 �0.05 to 0.42 1.52 22.24

Sensory impairment 9 .31 0.03 to 0.58 2.17* 5.48

Sickle cell disease 24 .04 �0.14 to 0.22 0.40 19.94

Spina bifida 9 .30 0.03 to 0.58 2.14* 2.84

Other illnesses/mixed samples 83 .34 0.25 to 0.44 7.00*** 97.00

Mean age QB(1,443)¼0.67

�12 years 175 .16 0.09 to 0.24 4.45*** 196.70

>12 years 270 .20 0.15 to 0.26 6.89*** 260.66

Percentage of girls QB(2,392)¼8.97*

<33.3% 48 .16 0.03 to 0.30 2.33* 46.66

33.3–66.6% 290 .15 0.10 to 0.21 5.47*** 282.44

>66.6% 57 .36 0.24 to 0.49 5.65*** 75.98

Percentage of members of ethnic minorities QB(1,175)¼2.63

<Mean 83 .14 0.03 to 0.24 2.55** 104.90*

>Mean 94 .19 0.07 to 0.32 3.63*** 65.09

Country QB(1,449)¼8.12*

Developing/threshold countries 41 .40 0.25 to 0.54 5.33*** 32.30

Developed countries 410 .17 0.13 to 0.22 7.20*** 431.40

Year of publication QB(2,448)¼9.81**

<1990 55 .29 0.16 to 0.42 4.29*** 55.84

1990–1999 128 .08 �0.00 to 0.17 1.86 138.37

2000–2010 268 .23 0.17 to 0.29 7.75*** 268.26

Rater of depressive symptoms QB(3,444)¼38.32***

Child/adolescent 336 .12 0.07 to 0.17 4.67*** 381.33*

Parent 60 .50 0.38 to 0.62 8.24*** 44.79

Teacher 7 .15 �0.19 to 0.49 0.89 3.33

Clinician 47 .34 0.21 to 0.48 5.05*** 34.50

Assessment of depression QB(7,439)¼67.18***

Beck Depression Inventory/Beck Youth Inventory 41 .24 0.10 to 0.38 3.34*** 43.22

Behavior Assessment System for Children 39 .17 0.03 to 0.31 2.38* 23.61

CBCL: Affective problems 13 .69 0.45 to 0.94 5.52*** 13.37

Child Depression Inventory 203 .03 �0.04 to 0.09 0.83 228.03

Depression scale of the MMPI 10 .60 0.28 to 0.92 3.74*** 4.90

Revised Child Anxiety and Depression Scale 6 .06 �0.30 to 0.41 0.31 4.07

Structured clinical interview 46 .33 0.20 to 0.46 5.11*** 36.37

Other measures 89 .36 0.26 to 0.45 7.40*** 105.25

(continued)

Depression and Chronic Illness 379

type headache, epilepsy, and spina bifida. However, no

significant between-group differences were found for arthri-

tis/rheumatism, cancer, cystic fibrosis, diabetes, heart dis-

eases, HIV infection/AIDS, inflammatory bowel disease,

and sickle cell disease. Health status explained between

0% (sickle cell disease) and 18.1% (chronic fatigue syn-

drome) of the variance of depressive symptoms.

According to the BESD, 71.3% of children with chronic

fatigue syndrome show depressive symptoms above the

median, as compared to 28.7% in healthy controls. In ad-

dition, 64.1% of children with fibromyalgia show depres-

sive symptoms above the median, but only 35.9% of their

healthy peers. As indicated by the non-overlap of the 95%

CIs, between-group differences were stronger for chronic

fatigue syndrome than for arthritis, asthma, cancer, cystic

fibrosis, diabetes, epilepsy, heart disease, HIV infection,

inflammatory bowel disease, sensory impairment, sickle

cell disease, and spina bifida. Differences were also stron-

ger for fibromyalgia and migraine/tension-type head ache

than for arthritis, asthma, cancer, cystic fibrosis, diabetes,

HIV infection, and sickle cell disease. In addition, differ-

ences were stronger for epilepsy than for arthritis, cancer,

cystic fibrosis, diabetes, and sickle cell disease.

Furthermore, differences were stronger for cleft lip and

palate than for arthritis, cancer, cystic fibrosis, and

diabetes.

The size of between-group differences did not vary by

age and race/ethnic minority status. We also checked

whether the results would differ between studies that in-

cluded some young adults and studies that exclusively fo-

cused on adolescents, and found no significant differences

[Q(1,256)¼0.21, NS]. However, larger between-group dif-

ferences were found in samples with higher percentages of

girls. Larger differences were also found in studies from

developing countries than from developed countries and

for studies published before 1990 than in studies that were

published in the 1990s. In line with our expectations,

between-group differences were stronger in studies that

used parent ratings of depressive symptoms than in studies

that used child reports. In addition, differences were stron-

ger when clinician-ratings rather than child ratings were

used. Regarding measures used, between-group differences

were stronger in studies that used the Affective Problems

scale of the CBCL than in other studies. Between-group

differences were also stronger when using the Beck

Depression Inventory/Beck Youth Inventory, the depres-

sion scale of the MMPI, or structured clinical interviews

than when using the CDI.

Because the lack of significant effect size on the CDI

may indicate that this measure might not be sensitive for

depressive symptoms of young people with chronic ill-

nesses, we also checked whether the results would be con-

sistent in studies that compared children with chronic

illness to test norms and to healthy control groups.

Children with chronic physical illness reported higher

CDI scores than healthy members of the control group

(d¼ .29, 95% CIs .19–.39, Z¼5.69, p < .001). However,

the reverse was true when comparing them to test norms

(d¼–.20, CI –0.26 to –0.14, Z¼–5.84, p < .001). These

results indicate that the CDI norms reported by Twenge

and Nolen-Hoeksema (2002) may overestimate the preva-

lence of depressive symptoms in general populations, and

researchers should collect data from a healthy control

group. We also checked whether our results would

change if we use the test norms by Kovacs (1992) but

our results remained unchanged.

Table I. Continued

Total difference

k d 95% CI Z Qw 450 .19 0.15 to 0.23 9.28*** 577.72***

Duration of illness QB(1,179)¼0.97

<Median (4.7 years) 91 .21 0.11 to 0.32 3.97*** 99.55

>Median 90 .14 0.03 to 0.24 2.57* 84.86

Representativeness of the sample QB(1,449)¼8.04*

Convenience sample (clinical sample) 412 .17 0.13 to 0.22 7.19*** 426.11

Random sample/community sample 39 .39 0.25 to 0.54 5.33*** 38.38

Basis of comparison QB(2,446)¼45.39***

Control group 241 .33 0.27 to 0.39 10.89*** 236.95

Test norms 207 .03 �0.03 to 0.10 1.00 223.25

Equivalence of patients and control group QB(2,234)¼0.13

No 31 .33 0.17 to 0.49 4.09*** 25.63

Yes 109 .32 0.23 to 0.40 7.04*** 122.14

Not tested 97 .34 0.25 to 0.43 7.22*** 94.60

Note. k¼number of studies; d¼effect size; Z¼ test for significance of d. 95% CI¼ lower and upper limits of 95% confidence interval; Qw/Qb¼ test for homogeneity of

effect sizes within (w) and between (b) groups. *p < .05, **p < .01, ***p < .001.

380 Pinquart and Shen

Illness duration did not moderate the size of

between-group differences, but this information was avail-

able only for about one third of the included studies.

Similarly, the equivalence of patient group and control

group had no significant moderating effect. However,

effect sizes varied by the representativeness of the sample

and by target of comparison. Stronger between-group dif-

ferences were found in studies with representative samples

than in those with convenience samples, and in studies

that compared young people with chronic illnesses against

a healthy control group.

Finally, because the moderator variables may not be

independent from each other, we checked whether the ob-

served bivariate moderator effects would persist in multi-

variate analysis. We included study characteristics with

significant univariate moderating effects. Because of the

large number of types of illnesses that were compared,

we could not include this variable in the multivariate anal-

ysis. As shown in Table II, the effects of gender, year of

publication, rater, CDI, country, and target of comparison

remained significant in multivariate analysis. However, the

effect of representativeness of the sample was no longer

significant in multivariate analysis.

Discussion

The present meta-analysis shows that young people with

chronic physical illnesses have, on average, higher levels of

depressive symptoms than their healthy peers. However,

this difference varies by the kind of illness, country,

gender, rater of depressive symptoms, method of assessing

depressive symptoms, year of publication, and target of

comparison. This study goes beyond previous

meta-analysis and narrative reviews by testing whether

the levels of depressive symptoms differ between types of

illness and whether the effect size is influenced by a large

number of study characteristics.

When comparing different kinds of illness, we found

that the effect sizes were quite divergent and impressive for

some of these illnesses. Depressive symptoms were highest

in chronic fatigue syndrome, diseases characterized by

chronic pain (fibromyalgia, migraine/tension-type head-

ache), cleft lip and palate, and epilepsy diseases that

were not analyzed in the previous meta-analysis.

There has been a debate about whether the visibility

and social consequences of a disease, restrictions of posi-

tive activities, brain dysfunction associated with some

kinds of illnesses, side effects of treatments, or specific

symptoms of illnesses, such as pain, have the strongest

effect on psychological health. Although these factors are

difficult to compare across illnesses and patient samples,

our results indicate that the strongest effect sizes are found

if more than one of these factors occur simultaneously.

Chronic fatigue syndrome is associated with tiredness

and restrictions of positive activities, alterations in brain

physiology and associated cognitive difficulties, and often

with headaches and muscle aches (Afari & Buchwald,

2003). In addition, symptom overlap of chronic fatigue

syndrome and depression may play a role because the

CDI (Kovacs, 1992) contains items on fatigue and de-

creased school performance.

Fibromyalgia showed the second highest effect size,

and is characterized by chronic widespread pain as well

as associated restrictions of positive activities. In addition,

neurophysiological changes and cognitive dysfunction are

found, as indicated by impaired concentration and

memory problems (e.g., Glass, 2006). Similarly, migraine

and tension-type headache are a significant detriment to

daily functioning and productivity (Roth-Isigkeit et al.,

2006).

Whereas the co-occurrence of more than one factor

could be suggested for explaining the elevated depressive

symptoms in four out of five chronic illnesses with the

highest effect sizes (chronic fatigue syndrome,

Table II. Multivariate Test for Moderating Effects (weighted multiple linear regression analysis)

Variable B b Z p

Percentage girls (1¼66% and higher, 0¼others) .16 .15 3.50 .001

Publication before 1990 (1¼yes, 0¼no) .13 .10 2.31 .03

Developed county (1¼yes, 0¼no) �.09 �.11 �2.50 .02

Child rating (1¼yes, 0¼no) �.14 �.13 �2.61 .01

CDI (1¼yes, 0¼no) �.18 �.18 �3.83 .001

Comparison with test norm (1¼yes, 0¼no) �.23 �.23 �5.23 .001

Representativeness of the sample .05 .03 0.74 .46

Constant 1.17 7.20 .001

R2 .21

N 436

Note. B (b)¼ (un-)standardized regression coefficient. R2¼explained variance.

Depression and Chronic Illness 381

fibromyalgia, migraine/tension-type headache, epilepsy),

there seems to be only one main explanation for elevated

levels of depressive symptoms in young people with cleft

lip and palate. Their symptoms probably reflect concerns

about appearance and negative social consequences (such

as being teased or rejected because of visible deformities

and speech abnormalities; e.g., De Sousa et al., 2009). In

fact, many adolescents with congenital and acquired facial

differences report stigma experiences, such as being teased

about how their face looks (Strauss et al., 2007).

In addition to explanations for above average effect

sizes, is has to be explained why young people with arthri-

tis, cancer, cystic fibrosis, diabetes, HIV infection, and

sickle cell disease did not show higher levels of depressive

symptoms than their healthy peers. The lack of elevated

average levels of depressive symptoms in some kinds of

illness may be based on the fact that many young patients

experience few or even no symptoms of their disease. For

example, many participants of studies on HIV infection

and AIDS were HIV positive without experiencing symp-

toms of AIDS. Similarly, many children and adolescents

with sickle cell disease are free of painful episodes and

other severe symptoms for longer time intervals (Telfer et

al., 2007). In addition, many children with juvenile arthri-

tis experience prolonged periods of low levels of disease

activity or even complete remission due to the develop-

ment of new therapeutic agents (Ravelli & Martini, 2006).

The lack of elevated levels of depressive symptoms in

patients with cancer and cystic fibrosis replicates previous

findings (Bennett, 1994). Because both kinds of illness are

life-threatening, patients may respond with denial in order

to protect their psychological well-being. Nonetheless,

Phipps, Steele, Hall, and Leigh (2001) did not find differ-

ences in the levels of defensiveness of cancer patients and

children with other chronic illnesses. Another explanation

may be that a larger number of studies focused on cancer

survivors who have already successfully completed their

therapy and may, therefore, no longer show elevated

levels of distress. In fact, Jorngarden, Mattsson, and von

Essen (2007) reported that adolescent cancer patients had

higher levels of depressive symptoms than healthy peers 6

months after being diagnosed but lower levels at the

18-month follow-up. Unfortunately, we could not include

the time since completion of therapy in our meta-analysis,

because too few studies provided this information.

Because the moderator effects of gender, country, year

of publication, and target of comparison were in line with

our expectations, they do not need not be discussed here.

In addition to comparisons of child ratings and parent

ratings (Bennett, 1994), we added an analysis of clinician

ratings and teacher ratings. Because the effect sizes were

lower for child ratings than for parent and clinician ratings,

our results may support the suggestion that children with

chronic illness underreport depressive symptoms or that

parents and clinicians overreport depressive symptoms.

However, because different measures were used for child,

parent, and clinician ratings, we cannot rule out the pos-

sibility that the different effect sizes were caused by

different methods of assessment.

Because the univariate effect of the representativeness

of the sample was lost in multivariate analysis, we conclude

that this effect was based on a confounding variable (the

use of control groups rather than test norms in

community-based studies with representative samples).

Limitations and Conclusions

Some limitations of the present meta-analysis need to be

mentioned. First, too few studies were available for sepa-

rately analyzing depressive symptoms in some kinds of

chronic illness, such as renal failure or congenital heart

disease. Second, we analyzed cross-sectional data that did

not allow for causal interpretation. The observed associa-

tions between chronic illness and depressive symptoms

may indicate that chronic illness is a risk factor for depres-

sive symptoms, but that depression may also affect the

course of chronic illness (e.g., Helgeland, Sandvik,

Mathiesen, & Kristensen, 2010), for example as mediated

by a delay of seeking medical help and low compliance

with medical procedures. In addition, third variables,

such as living in poverty, may increase the risk for both

chronic illness and depressive symptoms. Third, we could

not test for some moderators, such as time since last treat-

ment (because this information was rarely reported) or se-

verity of the disease (which would be difficult to compare

across different kinds of illness). Fourth, we could not an-

alyze the processes that link chronic illness with depressive

symptoms, such as metabolic changes, changes in activity

patterns, or social stigmatization. Fifth, we focused on de-

pressive symptoms rather than on depression diagnosis

because too few studies were available that provided com-

parative data on the frequency of clinical depression.

Finally, we assessed only one outcome variable. Effects

on other variables (such as externalizing problem behav-

iors) have to be analyzed in future meta-analyses.

Nonetheless, some important conclusions can be

drawn from the present meta-analysis. First, the small

average differences between the levels of depressive symp-

toms in children with and without chronic illness indicate

that many young people with chronic physical illnesses are

well-adapted and resilient. Although average differences

382 Pinquart and Shen

between depressive symptoms of children with and with-

out chronic physical illnesses are small to very small in a

statistical sense, most effect sizes are practically meaningful

when using Cohen’s criteria for interpreting effect sizes or

the BESD. Second, we conclude from the comparisons of

levels of depressive symptoms across different kinds of ill-

nesses that there are not only common effects of chronic

illnesses (which would cause similar levels of depressive

symptoms irrespective of the kind of chronic illness), but

also illness-specific effects.

Third, we conclude that children with chronic fatigue

syndrome, fibromyalgia, migraine or tension-type head-

ache, cleft lip and palate, and epilepsy are at highest risk

for developing depressive symptoms. Thus, pediatricians

and others who work with these children should be

aware of symptoms of psychological distress and make ap-

propriate referrals for mental health services when needed.

Fourth, because children and adolescents reported lower

levels of depressive symptoms than their parents and cli-

nicians, we recommend not to exclusively rely on child

ratings. We also recommend using healthy peers as control

group when working with the CDI.

With regard to future research, more research is

needed that specifies the conditions under which children

with chronic illnesses show elevated levels of psychological

distress and that provides empirically supported explana-

tions as to why some kinds of illness seem not to cause

elevated levels of depressive symptoms. Similarly, more

longitudinal studies are needed that analyze the extent to

which chronic illness affects the course of depressive symp-

toms and depressive symptoms affect the course of the

chronic illness. Furthermore, more studies are recom-

mended on depressive symptoms in those chronic illnesses

that could not be compared in our meta-analysis.

Supplementary Data

Supplementary data can be found at: http://www.jpepsy.

oxfordjournals.org/.

Conflicts of interest: None declared.

References

Achenbach, T. M. (1991). Manual for the child behavior

checklist/4-18 and 1991 profile. Burlington, VT:

University of Vermont.

Achenbach, T. M., Dumenci, L., & Rescorla, L. A.

(2003). DSM-oriented and empirically based

approaches to constructing scales from the same

item pools. Journal of Clinical Child and Adolescent

Psychology, 32, 328–340.

Afari, N., & Buchwald, D. (2003). Chronic fatigue syn-

drome: A review. American Journal of Psychiatry, 160,

221–236.

Beck, J. S., Beck, A. T., & Jolly, J. (2001). Manual for the

Beck Youth Inventories of Emotional and Social

Impairment. San Antonio, TX: Psychological

Corporation.

Bennett, D. S. (1994). Depression among children with

chronic medical problems: A meta-analysis. Journal

of Pediatric Psychology, 19, 149–169.

Bleyer, W. A. (2002). Cancer in older adolescents and

young adults. Medical and Pediatric Oncology, 38,

1–10.

Cohen, J. (1988). Statistical power analysis for the behav-

ioral sciences. Hillsdale: Erlbaum.

De Sousa, A., Devare, S., & Ghanshani, J. (2009).

Psychological issues in cleft lip and cleft palate.

Journal of Indian Association of Pediatric Surgeons, 14,

55–58.

Duval, S. J., & Tweedie, R. L. (2000). Trim and fill: A

simple funnel plot-based method of testing and

adjusting for publication bias in meta-analysis.

Biometrics, 56, 455–463.

Eccleston, C., Crombez, G., Scotford, A., Clinch, J., &

Connell, H. (2004). Adolescent chronic pain:

Patterns and predictors of emotional distress in

adolescents with chronic pain and their parents.

Pain, 108, 221–229.

Emslie, G. J., & Mayes, T. L. (1999). Depression in chil-

dren and adolescents: A guide to diagnosis and treat-

ment. CNS Drugs, 11, 181–189.

Glass, J. M. (2006). Cognitive dysfunction in fibromyalgia

and chronic fatigue syndrome: New trends and

future directions. Current Rheumatology Reports, 8,

425–429.

Helgeland, H., Sandvik, L., Mathiesen, K. S., &

Kristensen, H. (2010). Childhood predictors of recur-

rent abdominal pain in adolescence: A 13-year

population-based prospective study. Journal of

Psychosomatic Research, 68, 359–367.

Holmbeck, G. N., Johnson, S. Z., Wills, K. E.,

McKernon, W., Rose, B., Erklin, S., & Kemper, T.

(2002). Observed and perceived parental

overprotection in relation to psychosocial ad-

justment in preadolescents with a physical

disability: The mediational role of behavioral autono-

my. Journal of Consulting and Clinical Psychology, 70,

96–110.

Jorngarden, A., Mattsson, E., & von Essen, L. (2007).

Health-related quality of life, anxiety and depression

among adolescents and young adults with cancer: A

Depression and Chronic Illness 383

prospective longitudinal study. European Journal of

Cancer, 43, 1952–1958.

Kovacs, M. (1992). The Child Depression Inventory (CDI).

New York: Multi-health Systems.

Lipsey, M. W., & Wilson, D. B. (2001). Practical

Meta-Analysis. Thousand Oaks, CA: Sage.

Miller, J. M., Kustra, R. P., Vuong, A., Hammer, A. E., &

Messenheimer, J. A. (2008). Depressive symptoms in

epilepsy: prevalence, impact, aetiology, biological cor-

relates and effect of treatment with antiepileptic

drugs. Drugs, 68, 1493–1509.

Perrin, J. M., Bloom, S. R., & Gortmaker, S. L. (2007).

Increasing childhood chronic conditions in the

United States. JAMA, 297, 2755–2759.

Phipps, S., Steele, R. C., Hall, K., & Leigh, L. (2001).

Repressive adaptation in children with cancer: A rep-

lication and extension. Health Psychology, 6,

445–451.

Piccinelli, M., & Wilkinson, G. (2000). Gender differ-

ences in depression. British Journal of Psychiatry, 177,

486–492.

Plioplys, S. (2003). Depression in children and adoles-

cents with epilepsy. Epilepsy and Behavior, 4,

S39–S45.

Reynolds, C. R., & Kamphaus, R. W. (2004). Behavior

Assessment System for Children (2nd ed.). Circle

Pines, MN: American Guidance Service.

Rosenthal, R., & Rubin, D. B. (1982). A simple, general

purpose display of magnitude of experimental effect.

Journal of Educational Psychology, 74, 166–169.

Roth-Isigkeit, A., Thyen, U., Stöven, H.,

Schwarzenberger, J., & Schmucker, P. (2005). Pain

among children and adolescents: Restrictions in daily

living and triggering factors. Pediatrics, 115,

e152–e162.

Sandstrom, M. J., & Schanberg, L. E. (2004). Peer rejec-

tion, social behavior, and psychological adjustment

in children with juvenile rheumatic disease. Journal

of Pediatric Psychology, 29, 29–34.

Skinner, E. A., & Zimmer-Gembeck, M. J. (2007). The

development of coping. Annual Review of Psychology,

58, 119–144.

Stein, R. E., & Jessop, D. J. (1982). A non-categorical

approach to chronic childhood illness. Public Health

Reports, 97, 354–362.

Strauss, R. P., Ramsey, B. L., Edwards, T. C.,

Topolski, T. D., Kapp-Simon, K. A., Thomas, C. F.,

. . . Patrick, D. L. (2007). Stigma experiences in

youth with facial differences: A multi-site study of

adolescents and their mothers. Orthodontics &

Craniofacial Research, 10, 96–103.

Suris, J. C., Michaud, P. A., & Viner, R. (2004). The ado-

lescent with a chronic condition. Part I:

Developmental issues. Archive of Diseases in

Childhood, 89, 938–942.

Telfer, P., Coen, P., Chakravorty, S., Wilkey, O.,

Evans, J., Newell, H., . . . Kirkham, F. (2007).

Clinical outcomes in children with sickle cell disease.

Haematologica, 92, 905–912.

Tellegen, A., Ben-Porath, Y. S., McNulty, J. L., Arbisi, P.

A., Graham, J. R., & Kaemmer, B. (2003). The

MMPI-2 Restructured Clinical Scales: Development,

Validation, and Interpretation. Minneapolis, MN:

University of Minnesota Press.

Twenge, J. M., & Nolen–Hoeksema, S. (2002). Age,

gender, race, socioeconomic status, and birth cohort

difference on the children’s depression inventory: A

meta-analysis. Journal of Abnormal Psychology, 111,

578–588.

van der Lee, J., Mokkink, L. B., Grootenhuis, M. A.,

Heymans, H. S., & Offringa, M. (2007). Definitions

and measurement of chronic health conditions in

childhood: A systematic review. JAMA, 29,

2741–2751.

World Bank (2010). Country and Lending Groups.

Retrieved From http://data.worldbank.org/ about/

country-classifications/country-and-lending-groups.

384 Pinquart and Shen

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